Malformaciones linfáticas cervicofaciales con compresión de la vía aérea. Reporte de cuatro casos
Article Sidebar
Main Article Content
Abstract
Lymphangiomas are rare, benign congenital lesions resulting from abnormal development of the lymphatic system. The literature reports an incidence of 1 in every 2000 to 4000 live births. Despite being benign, they can present with serious complications such as airway obstruction, stridor, apnea, cyanosis, and progressive dyspnea. The treatment approach remains controversial, with options mentioned in case series reviews including surgery, sclerotherapy, immunosuppressants, or a combination of these. This case report discusses four patients: two neonates and two school-aged children, who experienced extrinsic airway compression. These patients were treated with intralesional sclerotherapy using bleomycin, and in two cases, this was combined with surgery. Given the extensive nature of the lesions, the rarity of life-threatening complications, and the combined treatment modalities, this report of these four patients is considered significant.
Key words: Lymphangiomas – sclerotherapy – bleomycin
Downloads
Article Details
This work is licensed under a Creative Commons Attribution-NonCommercial-ShareAlike 4.0 International License.
References
Grasso, D. L., Pelizzo, G., Zocconi, E., & Schleef, J. (2008). Lymphangiomas of the head and neck in children. Acta Otorhinolaryngologica Italica, 28(1), 17.
Lu, D., Wang, Y., Zeng, W., & Peng, B. (2015). Giant fetal lymphangioma at chest wall and prognosis: Case report and literature review. Taiwanese Journal of Obstetrics & Gynecology, 54(1), 62–65. https://doi.org/10.1016/j.tjog.2014.11.009
García C., K., Reyes S., G., Petit-Breuilh S., V., & Alvo V., A. (2020). Malformaciones vasculares linfáticas de cabeza y cuello en pacientes pediátricos: revisión de la literatura. Revista de Otorrinolaringología y Cirugía de Cabeza y Cuello, 80(4), 554–561. https://doi.org/10.4067/s0718-48162020000400554
Guerra Macías, I. (Ed.). (2021). Revisión de la conducta quirúrgica del linfangioma quístico (Vol. 22, Número 1). Revista Cubana de Angiología y Cirugía Vascular. https://www.medigraphic.com/pdfs/revcubangcirvas/cac-2021/cac211i.pdf
Galvez Ramirez Victoria, Medina Quevedo Milton, Cáceres Aucatoma Freud. (2021). Vista de Evaluación del tratamiento de linfangiomas con bleomicina en población pediátrica de 0 a 18 años. Revista HCAM, 20(2), 53–59. https://doi.org/10.36015/cambios.v20.n2.2021.353
Molino, J. A., Guillén, G., Peiró, J. L., García-Vaquero, J. A., Marhuenda, C., Carreras, E., Lloret, J., & Martínez-Ibáñez, V. (2010). Linfangioma quístico cervical: todavía un reto. Secipe.org. https://www.secipe.org/coldata/upload/revista/2010_23-3_147-152.pdf
Cuervo J. Malformaciones linfáticas: tratamiento percutáneo con bleomicina [Internet]. Available from: http://www.scielo.org.ar/scielo.php?pid=S0325-00752011000500008&script=sci_arttext&tlng=en
Asociación Española de Pediatría. Bleomicina | Asociación Española de Pediatría [Internet]. Available from: https://www.aeped.es/comite-medicamentos/pediamecum/bleomicina
Sierre S, Teplisky D, Lipsich J. Malformaciones vasculares: actualización en diagnóstico por imágenes y tratamiento [Internet]. Available from: http://www.scielo.org.ar/scielo.php?pid=S0325-00752016000200013&script=sci_arttext
Cruz-Martínez R, Méndez A, Pineda-Alemán H, Rebolledo-Fernández C. Técnica EXIT (Ex Utero Intrapartum Treatment): indicaciones, limitaciones, riesgos y evolución a la técnica de intubación traqueal fetal endoscópica (FETI). Ginecol Obstet Mex 2015;83:58-65